Mapping Anatomical Cerebellar Changes and their Neurocognitive Manifestations in SCA34: A Detailed Case Analysis
(2025) PSYP01 20251Department of Psychology
- Abstract
- Spinocerebellar Ataxia Type 34 is a rare hereditary ataxia characterised by progressive cerebellar degeneration, motor impairment, and dermatological features, with cognitive manifestations remaining poorly understood. This case report presents neurocognitive and neuroimaging profiles of two Swedish male patients with genetically confirmed SCA34. Both underwent an extensive neuropsychological test battery and ultra-high-field 7T MRI scanning, enabling fine-grained measurement of cerebellar cortical thickness using both traditional lobular and functional parcellations. In both patients, cortical thinning was observed compared to an age- and sex-matched control, most prominently in Crus I/II and lobule VI. These reductions were descriptively... (More)
- Spinocerebellar Ataxia Type 34 is a rare hereditary ataxia characterised by progressive cerebellar degeneration, motor impairment, and dermatological features, with cognitive manifestations remaining poorly understood. This case report presents neurocognitive and neuroimaging profiles of two Swedish male patients with genetically confirmed SCA34. Both underwent an extensive neuropsychological test battery and ultra-high-field 7T MRI scanning, enabling fine-grained measurement of cerebellar cortical thickness using both traditional lobular and functional parcellations. In both patients, cortical thinning was observed compared to an age- and sex-matched control, most prominently in Crus I/II and lobule VI. These reductions were descriptively consistent with deficits in executive functioning, working memory, and visuospatial processing, consistent with Cerebellar Cognitive Affective Syndrome. One patient presented longer disease duration and greater motor impairment, as well as more severe cortical thinning and broader cognitive impairments, descriptively aligning with a correspondence between structural and functional disease severity. While exploratory analyses using functional (MDTB) parcellations provided complementary perspectives, results were constrained by methodological challenges including segmentation artifacts and atlas misalignments. Overall, the findings provide the first high-resolution mapping of cerebellar cortical thickness in SCA34 and underscore the importance of integrating advanced neuroimaging with neurocognitive profiling to clarify the cerebellum’s role in cognition. (Less)
Please use this url to cite or link to this publication:
http://lup.lub.lu.se/student-papers/record/9215205
- author
- Kirchhoff, Lena LU
- supervisor
- organization
- course
- PSYP01 20251
- year
- 2025
- type
- H2 - Master's Degree (Two Years)
- subject
- keywords
- SCA34, cerebellar cortical thickness, cerebellum, CCAS, MDTB-atlas
- language
- English
- id
- 9215205
- date added to LUP
- 2025-11-12 16:30:58
- date last changed
- 2025-11-12 16:30:58
@misc{9215205,
abstract = {{Spinocerebellar Ataxia Type 34 is a rare hereditary ataxia characterised by progressive cerebellar degeneration, motor impairment, and dermatological features, with cognitive manifestations remaining poorly understood. This case report presents neurocognitive and neuroimaging profiles of two Swedish male patients with genetically confirmed SCA34. Both underwent an extensive neuropsychological test battery and ultra-high-field 7T MRI scanning, enabling fine-grained measurement of cerebellar cortical thickness using both traditional lobular and functional parcellations. In both patients, cortical thinning was observed compared to an age- and sex-matched control, most prominently in Crus I/II and lobule VI. These reductions were descriptively consistent with deficits in executive functioning, working memory, and visuospatial processing, consistent with Cerebellar Cognitive Affective Syndrome. One patient presented longer disease duration and greater motor impairment, as well as more severe cortical thinning and broader cognitive impairments, descriptively aligning with a correspondence between structural and functional disease severity. While exploratory analyses using functional (MDTB) parcellations provided complementary perspectives, results were constrained by methodological challenges including segmentation artifacts and atlas misalignments. Overall, the findings provide the first high-resolution mapping of cerebellar cortical thickness in SCA34 and underscore the importance of integrating advanced neuroimaging with neurocognitive profiling to clarify the cerebellum’s role in cognition.}},
author = {{Kirchhoff, Lena}},
language = {{eng}},
note = {{Student Paper}},
title = {{Mapping Anatomical Cerebellar Changes and their Neurocognitive Manifestations in SCA34: A Detailed Case Analysis}},
year = {{2025}},
}