Abnormal hyperactivity of specific striatal ensembles encodes distinct dyskinetic behaviors revealed by high-resolution clustering
(2025) In Cell Reports 44(7).- Abstract
L-DOPA-induced dyskinesia (LID) is a debilitating complication of dopamine replacement therapy in Parkinson's disease and the most common hyperkinetic disorder of basal ganglia origin. Abnormal activity of striatal D1 and D2 spiny projection neurons (SPNs) is critical for LID, yet the link between SPN activity patterns and specific dyskinetic movements remains unknown. To explore this, we implemented a data-driven method for clustering movements based on high-resolution motion sensors and video recordings. In a mouse model of LID, this method identified two main dyskinesia types and pathological rotations, all absent during normal behavior. Using single-cell-resolution imaging, we found that specific sets of both D1- and D2-SPNs were... (More)
L-DOPA-induced dyskinesia (LID) is a debilitating complication of dopamine replacement therapy in Parkinson's disease and the most common hyperkinetic disorder of basal ganglia origin. Abnormal activity of striatal D1 and D2 spiny projection neurons (SPNs) is critical for LID, yet the link between SPN activity patterns and specific dyskinetic movements remains unknown. To explore this, we implemented a data-driven method for clustering movements based on high-resolution motion sensors and video recordings. In a mouse model of LID, this method identified two main dyskinesia types and pathological rotations, all absent during normal behavior. Using single-cell-resolution imaging, we found that specific sets of both D1- and D2-SPNs were abnormally active during these pathological movements. Under baseline conditions, these SPN sets were active during behaviors sharing physical features with LID movements. These findings indicate that ensembles of behavior-encoding D1- and D2-SPNs form new combinations of hyperactive neurons mediating specific dyskinetic features.
(Less)
- author
- Alcacer, Cristina
LU
; Klaus, Andreas
; Mendonça, Marcelo
; Abalde, Sara F
; Cenci, Maria Angela
LU
and Costa, Rui M
- organization
- publishing date
- 2025-07-22
- type
- Contribution to journal
- publication status
- published
- subject
- keywords
- Animals, Mice, Corpus Striatum/physiopathology, Receptors, Dopamine D1/metabolism, Levodopa/adverse effects, Receptors, Dopamine D2/metabolism, Dyskinesia, Drug-Induced/physiopathology, Neurons/metabolism, Male, Disease Models, Animal, Mice, Inbred C57BL, Parkinson Disease, Behavior, Animal
- in
- Cell Reports
- volume
- 44
- issue
- 7
- article number
- 115988
- publisher
- Cell Press
- external identifiers
-
- scopus:105009909109
- pmid:40638389
- ISSN
- 2211-1247
- DOI
- 10.1016/j.celrep.2025.115988
- language
- English
- LU publication?
- yes
- additional info
- Published by Elsevier Inc.
- id
- 06452e0f-1134-4e3c-904e-f01b88cff401
- date added to LUP
- 2025-12-01 14:59:44
- date last changed
- 2025-12-16 05:34:53
@article{06452e0f-1134-4e3c-904e-f01b88cff401,
abstract = {{<p>L-DOPA-induced dyskinesia (LID) is a debilitating complication of dopamine replacement therapy in Parkinson's disease and the most common hyperkinetic disorder of basal ganglia origin. Abnormal activity of striatal D1 and D2 spiny projection neurons (SPNs) is critical for LID, yet the link between SPN activity patterns and specific dyskinetic movements remains unknown. To explore this, we implemented a data-driven method for clustering movements based on high-resolution motion sensors and video recordings. In a mouse model of LID, this method identified two main dyskinesia types and pathological rotations, all absent during normal behavior. Using single-cell-resolution imaging, we found that specific sets of both D1- and D2-SPNs were abnormally active during these pathological movements. Under baseline conditions, these SPN sets were active during behaviors sharing physical features with LID movements. These findings indicate that ensembles of behavior-encoding D1- and D2-SPNs form new combinations of hyperactive neurons mediating specific dyskinetic features.</p>}},
author = {{Alcacer, Cristina and Klaus, Andreas and Mendonça, Marcelo and Abalde, Sara F and Cenci, Maria Angela and Costa, Rui M}},
issn = {{2211-1247}},
keywords = {{Animals; Mice; Corpus Striatum/physiopathology; Receptors, Dopamine D1/metabolism; Levodopa/adverse effects; Receptors, Dopamine D2/metabolism; Dyskinesia, Drug-Induced/physiopathology; Neurons/metabolism; Male; Disease Models, Animal; Mice, Inbred C57BL; Parkinson Disease; Behavior, Animal}},
language = {{eng}},
month = {{07}},
number = {{7}},
publisher = {{Cell Press}},
series = {{Cell Reports}},
title = {{Abnormal hyperactivity of specific striatal ensembles encodes distinct dyskinetic behaviors revealed by high-resolution clustering}},
url = {{http://dx.doi.org/10.1016/j.celrep.2025.115988}},
doi = {{10.1016/j.celrep.2025.115988}},
volume = {{44}},
year = {{2025}},
}