Variants in the DDX6-CXCR5 autoimmune disease risk locus influence the regulatory network in immune cells and salivary gland
(2023) In bioRxiv : the preprint server for biology p.1-48- Abstract
Fine mapping and bioinformatic analysis of the DDX6-CXCR5 genetic risk association in Sjögren's Disease (SjD) and Systemic Lupus Erythematosus (SLE) identified five common SNPs with functional evidence in immune cell types: rs4938573, rs57494551, rs4938572, rs4936443, rs7117261. Functional interrogation of nuclear protein binding affinity, enhancer/promoter regulatory activity, and chromatin-chromatin interactions in immune, salivary gland epithelial, and kidney epithelial cells revealed cell type-specific allelic effects for all five SNPs that expanded regulation beyond effects on DDX6 and CXCR5 expression. Mapping the local chromatin regulatory network revealed several additional genes of interest, including lnc-PHLDB1-1.... (More)
Fine mapping and bioinformatic analysis of the DDX6-CXCR5 genetic risk association in Sjögren's Disease (SjD) and Systemic Lupus Erythematosus (SLE) identified five common SNPs with functional evidence in immune cell types: rs4938573, rs57494551, rs4938572, rs4936443, rs7117261. Functional interrogation of nuclear protein binding affinity, enhancer/promoter regulatory activity, and chromatin-chromatin interactions in immune, salivary gland epithelial, and kidney epithelial cells revealed cell type-specific allelic effects for all five SNPs that expanded regulation beyond effects on DDX6 and CXCR5 expression. Mapping the local chromatin regulatory network revealed several additional genes of interest, including lnc-PHLDB1-1. Collectively, functional characterization implicated the risk alleles of these SNPs as modulators of promoter and/or enhancer activities that regulate cell type-specific expression of DDX6, CXCR5, and lnc-PHLDB1-1, among others. Further, these findings emphasize the importance of exploring the functional significance of SNPs in the context of complex chromatin architecture in disease-relevant cell types and tissues.
(Less)
- author
- author collaboration
- organization
- publishing date
- 2023-10-06
- type
- Working paper/Preprint
- publication status
- published
- subject
- in
- bioRxiv : the preprint server for biology
- pages
- 1 - 48
- publisher
- bioRxiv
- external identifiers
-
- pmid:39071447
- ISSN
- 2692-8205
- DOI
- 10.1101/2023.10.05.561076
- language
- English
- LU publication?
- yes
- id
- 11b4320d-8116-4d7b-be05-b98adfa05dab
- date added to LUP
- 2025-01-23 12:31:39
- date last changed
- 2025-05-20 09:42:11
@misc{11b4320d-8116-4d7b-be05-b98adfa05dab, abstract = {{<p>Fine mapping and bioinformatic analysis of the DDX6-CXCR5 genetic risk association in Sjögren's Disease (SjD) and Systemic Lupus Erythematosus (SLE) identified five common SNPs with functional evidence in immune cell types: rs4938573, rs57494551, rs4938572, rs4936443, rs7117261. Functional interrogation of nuclear protein binding affinity, enhancer/promoter regulatory activity, and chromatin-chromatin interactions in immune, salivary gland epithelial, and kidney epithelial cells revealed cell type-specific allelic effects for all five SNPs that expanded regulation beyond effects on DDX6 and CXCR5 expression. Mapping the local chromatin regulatory network revealed several additional genes of interest, including lnc-PHLDB1-1. Collectively, functional characterization implicated the risk alleles of these SNPs as modulators of promoter and/or enhancer activities that regulate cell type-specific expression of DDX6, CXCR5, and lnc-PHLDB1-1, among others. Further, these findings emphasize the importance of exploring the functional significance of SNPs in the context of complex chromatin architecture in disease-relevant cell types and tissues.</p>}}, author = {{Wiley, Mandi M and Khatri, Bhuwan and Joachims, Michelle L and Tessneer, Kandice L and Stolarczyk, Anna M and Rasmussen, Astrid and Anaya, Juan-Manuel and Aqrawi, Lara A and Bae, Sang-Cheol and Baecklund, Eva and Björk, Albin and Brun, Johan G and Bucher, Sara Magnusson and Dand, Nick and Eloranta, Maija-Leena and Engelke, Fiona and Forsblad-d'Elia, Helena and Fugmann, Cecilia and Glenn, Stuart B and Gong, Chen and Gottenberg, Jacques-Eric and Hammenfors, Daniel and Imgenberg-Kreuz, Juliana and Jensen, Janicke Liaaen and Johnsen, Svein Joar Auglænd and Jonsson, Malin V and Kelly, Jennifer A and Khanam, Sharmily and Kim, Kwangwoo and Kvarnström, Marika and Mandl, Thomas and Martín, Javier and Morris, David L and Nocturne, Gaetane and Norheim, Katrine Brække and Olsson, Peter and Palm, Øyvind and Pers, Jacques-Olivier and Rhodus, Nelson L and Sjöwall, Christopher and Skarstein, Kathrine and Taylor, Kimberly E and Tombleson, Phil and Thorlacius, Gudny Ella and Venuturupalli, Swamy and Vital, Edward M and Wallace, Daniel J and Grundahl, Kiely M and Radfar, Lida and Brennan, Michael T}}, issn = {{2692-8205}}, language = {{eng}}, month = {{10}}, note = {{Preprint}}, pages = {{1--48}}, publisher = {{bioRxiv}}, series = {{bioRxiv : the preprint server for biology}}, title = {{Variants in the DDX6-CXCR5 autoimmune disease risk locus influence the regulatory network in immune cells and salivary gland}}, url = {{http://dx.doi.org/10.1101/2023.10.05.561076}}, doi = {{10.1101/2023.10.05.561076}}, year = {{2023}}, }