Cantú Syndrome With Acromegaloid Features, Multiple Endocrinopathies, and Infection Susceptibility
(2025) In JCEM case reports 3(5).- Abstract
Cantú syndrome involves fetal polyhydramniosis, congenital hypertrichosis, and macrosomia. Distinctive features include acromegaloid features with broad nasal bridge and macroglossia as well as cardiac abnormalities, including patent ductus arteriosus. We present a case in a male patient, who presented with cardiac abnormalities in childhood, but was diagnosed with the syndrome in adulthood after many years of atypical symptoms such as multiple endocrinopathies and infection susceptibility. He had surgery for a patent ductus arteriosus in early childhood. During adulthood, he developed idiopathic pericarditis. Extensive rheumatological investigations were made, and in parallel, several endocrinopathies were found. These included... (More)
Cantú syndrome involves fetal polyhydramniosis, congenital hypertrichosis, and macrosomia. Distinctive features include acromegaloid features with broad nasal bridge and macroglossia as well as cardiac abnormalities, including patent ductus arteriosus. We present a case in a male patient, who presented with cardiac abnormalities in childhood, but was diagnosed with the syndrome in adulthood after many years of atypical symptoms such as multiple endocrinopathies and infection susceptibility. He had surgery for a patent ductus arteriosus in early childhood. During adulthood, he developed idiopathic pericarditis. Extensive rheumatological investigations were made, and in parallel, several endocrinopathies were found. These included thyroiditis with subsequent hypothyroidism, idiopathic partial hypocortisolism, and GH insufficiency. In addition, he had mild neutropenia and required hospitalization twice because of Streptococcus pyogenes infections. Immunodeficiency screening has not revealed a specific primary immunodeficiency, yet transient neutropenia, low count of CD8+ effector memory T cells, as well as lymphocyte responses, was seen during bacteremia. The diagnose was made after a trio-whole genome sequencing identified a pathogenic missense variant of the gene ABCC9 (c.3460C > T;p. (Arg1154Trp)) causing Cantú syndrome.
(Less)
- author
- Nygren, David
LU
; Moll, Ulrika LU
; Braun, Oscar LU ; Karlsson, Ulf LU and Jönsson, Göran LU
- organization
-
- Teachers at the Medical Programme
- Infection Medicine (BMC)
- Translational infection medicine (research group)
- Diabetes lab (research group)
- Medicine/Emergency Medicine, Lund
- EXODIAB: Excellence of Diabetes Research in Sweden
- Heart Failure and Mechanical Support (research group)
- Molecular Epidemiology and Cardiology (research group)
- Cardiology
- publishing date
- 2025-05
- type
- Contribution to journal
- publication status
- published
- subject
- in
- JCEM case reports
- volume
- 3
- issue
- 5
- article number
- luaf068
- external identifiers
-
- pmid:40236613
- ISSN
- 2755-1520
- DOI
- 10.1210/jcemcr/luaf068
- language
- English
- LU publication?
- yes
- additional info
- © The Author(s) 2025. Published by Oxford University Press on behalf of the Endocrine Society.
- id
- 06f431e3-12f9-4fcd-be81-a2f45bbe9219
- date added to LUP
- 2025-05-28 12:09:47
- date last changed
- 2025-05-28 16:35:11
@article{06f431e3-12f9-4fcd-be81-a2f45bbe9219, abstract = {{<p>Cantú syndrome involves fetal polyhydramniosis, congenital hypertrichosis, and macrosomia. Distinctive features include acromegaloid features with broad nasal bridge and macroglossia as well as cardiac abnormalities, including patent ductus arteriosus. We present a case in a male patient, who presented with cardiac abnormalities in childhood, but was diagnosed with the syndrome in adulthood after many years of atypical symptoms such as multiple endocrinopathies and infection susceptibility. He had surgery for a patent ductus arteriosus in early childhood. During adulthood, he developed idiopathic pericarditis. Extensive rheumatological investigations were made, and in parallel, several endocrinopathies were found. These included thyroiditis with subsequent hypothyroidism, idiopathic partial hypocortisolism, and GH insufficiency. In addition, he had mild neutropenia and required hospitalization twice because of Streptococcus pyogenes infections. Immunodeficiency screening has not revealed a specific primary immunodeficiency, yet transient neutropenia, low count of CD8+ effector memory T cells, as well as lymphocyte responses, was seen during bacteremia. The diagnose was made after a trio-whole genome sequencing identified a pathogenic missense variant of the gene ABCC9 (c.3460C > T;p. (Arg1154Trp)) causing Cantú syndrome.</p>}}, author = {{Nygren, David and Moll, Ulrika and Braun, Oscar and Karlsson, Ulf and Jönsson, Göran}}, issn = {{2755-1520}}, language = {{eng}}, number = {{5}}, series = {{JCEM case reports}}, title = {{Cantú Syndrome With Acromegaloid Features, Multiple Endocrinopathies, and Infection Susceptibility}}, url = {{http://dx.doi.org/10.1210/jcemcr/luaf068}}, doi = {{10.1210/jcemcr/luaf068}}, volume = {{3}}, year = {{2025}}, }