LINE-1 retrotransposons mediate cis-acting transcriptional control in human pluripotent stem cells and regulate early brain development
(2025) In Cell Genomics- Abstract
Long interspersed nuclear element 1 (L1) retrotransposons represent a vast source of genetic variability. However, mechanistic analysis of whether and how L1s contribute to human developmental programs is lacking, in part due to the challenges associated with specific profiling and manipulation of human L1 expression. Here, we show that thousands of hominoid-specific L1 integrants are expressed in human induced pluripotent stem cells and cerebral organoids. The activity levels of individual L1 promoters vary widely and correlate with an active epigenetic state. Efficient on-target CRISPR interference (CRISPRi) silencing of L1s revealed nearly a hundred co-opted L1-derived chimeric transcripts, and L1 silencing resulted in changes in... (More)
Long interspersed nuclear element 1 (L1) retrotransposons represent a vast source of genetic variability. However, mechanistic analysis of whether and how L1s contribute to human developmental programs is lacking, in part due to the challenges associated with specific profiling and manipulation of human L1 expression. Here, we show that thousands of hominoid-specific L1 integrants are expressed in human induced pluripotent stem cells and cerebral organoids. The activity levels of individual L1 promoters vary widely and correlate with an active epigenetic state. Efficient on-target CRISPR interference (CRISPRi) silencing of L1s revealed nearly a hundred co-opted L1-derived chimeric transcripts, and L1 silencing resulted in changes in neural differentiation programs and reduced cerebral organoid size. Together, these data implicate L1s and L1-derived transcripts in hominoid-specific CNS developmental processes.
(Less)
- author
- organization
-
- Infect@LU
- StemTherapy: National Initiative on Stem Cells for Regenerative Therapy
- Molecular Neurogenetics (research group)
- MultiPark: Multidisciplinary research focused on Parkinson's disease
- Stem Cell Center
- Department Office of Experimental Medical Science
- Cell and Gene Therapy Core
- Epigenetics and Chromatin Dynamics (research group)
- Stem Cells, Aging and Neurodegeneration (research group)
- Developmental and Regenerative Neurobiology (research group)
- WCMM-Wallenberg Centre for Molecular Medicine
- Human Neural Developmental Biology (research group)
- LUCC: Lund University Cancer Centre
- publishing date
- 2025-08-19
- type
- Contribution to journal
- publication status
- epub
- subject
- in
- Cell Genomics
- article number
- 100979
- publisher
- Cell Press
- external identifiers
-
- scopus:105015173791
- pmid:40848716
- ISSN
- 2666-979X
- DOI
- 10.1016/j.xgen.2025.100979
- language
- English
- LU publication?
- yes
- additional info
- Copyright © 2025 The Authors. Published by Elsevier Inc. All rights reserved.
- id
- e1fa86e4-ebe0-4706-8b34-9f3c800da4a8
- date added to LUP
- 2025-08-28 13:57:16
- date last changed
- 2025-10-14 10:12:18
@article{e1fa86e4-ebe0-4706-8b34-9f3c800da4a8, abstract = {{<p>Long interspersed nuclear element 1 (L1) retrotransposons represent a vast source of genetic variability. However, mechanistic analysis of whether and how L1s contribute to human developmental programs is lacking, in part due to the challenges associated with specific profiling and manipulation of human L1 expression. Here, we show that thousands of hominoid-specific L1 integrants are expressed in human induced pluripotent stem cells and cerebral organoids. The activity levels of individual L1 promoters vary widely and correlate with an active epigenetic state. Efficient on-target CRISPR interference (CRISPRi) silencing of L1s revealed nearly a hundred co-opted L1-derived chimeric transcripts, and L1 silencing resulted in changes in neural differentiation programs and reduced cerebral organoid size. Together, these data implicate L1s and L1-derived transcripts in hominoid-specific CNS developmental processes.</p>}}, author = {{Adami, Anita and Garza, Raquel and Gerdes, Patricia and Johansson, Pia A and Dorazehi, Fereshteh and Koutounidou, Symela and Castilla-Vallmanya, Laura and Atacho, Diahann A M and Sharma, Yogita and Johansson, Jenny G and Tam, Oliver and Kirkeby, Agnete and Barker, Roger A and Hammell, Molly Gale and Douse, Christopher H and Jakobsson, Johan}}, issn = {{2666-979X}}, language = {{eng}}, month = {{08}}, publisher = {{Cell Press}}, series = {{Cell Genomics}}, title = {{LINE-1 retrotransposons mediate cis-acting transcriptional control in human pluripotent stem cells and regulate early brain development}}, url = {{http://dx.doi.org/10.1016/j.xgen.2025.100979}}, doi = {{10.1016/j.xgen.2025.100979}}, year = {{2025}}, }